TY - JOUR
T1 - Novel approach to a rare communicating anal canal duplication in an 11-month-old female
T2 - A case report
AU - Agathis, Alexandra Z.
AU - Abeshouse, Marnie
AU - Li, Linda
AU - Midulla, Peter
N1 - Publisher Copyright:
© 2023 The Authors
PY - 2023/8
Y1 - 2023/8
N2 - Background: Anal canal duplication (ACD) is a rare congenital anorectal malformation (ARM) with limited cases and surgical techniques described in the literature to date. Case summary: A full-term 8-month-old female with a history of constipation was referred to our pediatric surgery clinic for two patent anal orifices draining feculent material. Imaging established that these two openings converged into a common rectum separated by intervening tissue. Intraoperative sphincter mapping further confirmed that the sphincter complex completely encircled the posterior opening and partially surrounded the anterior opening, with viable contractile tissue within the dividing septum. An anoplasty procedure was performed, in which the intervening muscular tissue between the dual anal openings was divided and subcutaneously tunneled to construct a single, functioning neo-anus surrounded by sphincter muscle. There were no postoperative complications, and she continues to have a single, well-functioning anus. Conclusions: Anal canal duplication can be treated successfully with an anoplasty if sufficient sphincter muscle is present. Here, we present a perineal approach for joining two communicating anal openings with excellent results.
AB - Background: Anal canal duplication (ACD) is a rare congenital anorectal malformation (ARM) with limited cases and surgical techniques described in the literature to date. Case summary: A full-term 8-month-old female with a history of constipation was referred to our pediatric surgery clinic for two patent anal orifices draining feculent material. Imaging established that these two openings converged into a common rectum separated by intervening tissue. Intraoperative sphincter mapping further confirmed that the sphincter complex completely encircled the posterior opening and partially surrounded the anterior opening, with viable contractile tissue within the dividing septum. An anoplasty procedure was performed, in which the intervening muscular tissue between the dual anal openings was divided and subcutaneously tunneled to construct a single, functioning neo-anus surrounded by sphincter muscle. There were no postoperative complications, and she continues to have a single, well-functioning anus. Conclusions: Anal canal duplication can be treated successfully with an anoplasty if sufficient sphincter muscle is present. Here, we present a perineal approach for joining two communicating anal openings with excellent results.
KW - Anal duplication
KW - Anorectal malformation
KW - Case report
UR - http://www.scopus.com/inward/record.url?scp=85161658182&partnerID=8YFLogxK
U2 - 10.1016/j.epsc.2023.102677
DO - 10.1016/j.epsc.2023.102677
M3 - Article
AN - SCOPUS:85161658182
SN - 2213-5766
VL - 95
JO - Journal of Pediatric Surgery Case Reports
JF - Journal of Pediatric Surgery Case Reports
M1 - 102677
ER -