TY - JOUR
T1 - Germline variants in pancreatic cancer patients with a personal or family history of cancer fulfilling the revised Bethesda guidelines
AU - Ohmoto, Akihiro
AU - Morizane, Chigusa
AU - Kubo, Emi
AU - Takai, Erina
AU - Hosoi, Hiroko
AU - Sakamoto, Yasunari
AU - Kondo, Shunsuke
AU - Ueno, Hideki
AU - Shimada, Kazuaki
AU - Yachida, Shinichi
AU - Okusaka, Takuji
N1 - Publisher Copyright:
© 2018, Japanese Society of Gastroenterology.
PY - 2018/10/1
Y1 - 2018/10/1
N2 - Background: Pancreatic cancer (PC) is categorized as a neoplasm associated with Lynch syndrome; however, the precise proportion of PC patients harboring DNA mismatch repair genes (MMR genes) remains unclear, especially in the Asian population. Methods: Among 304 Japanese patients with pathologically proven pancreatic ductal adenocarcinoma, we selected 20 (6.6%) patients with a personal or family history involving first- or second-degree relatives fulfilling the revised Bethesda guidelines (RBG), defined as RBG-compatible cases. We analyzed germline variants in 21 genes related to a hereditary predisposition for cancer as well as clinical features in all 20 cases. Results: The RBG-compatible cases did not show any unique clinicopathological features. Targeted sequencing data revealed three patients carrying deleterious or likely deleterious variants. Specifically, these three patients harbored a nonsense variant in ATM, a frameshift variant in ATM, and a concurrent nonsense variant in PMS2 and missense variant in CHEK2 (double-mutation carrier), respectively. Although an MMR gene mutation was identified in only one of the 20 patients, up to 15% of the RBG-compatible PC cases were associated with germline deleterious or likely deleterious variants. Conclusions: These findings showed that these guidelines could be useful for identifying PC patients with DNA damage repair genes as well as MMR genes.
AB - Background: Pancreatic cancer (PC) is categorized as a neoplasm associated with Lynch syndrome; however, the precise proportion of PC patients harboring DNA mismatch repair genes (MMR genes) remains unclear, especially in the Asian population. Methods: Among 304 Japanese patients with pathologically proven pancreatic ductal adenocarcinoma, we selected 20 (6.6%) patients with a personal or family history involving first- or second-degree relatives fulfilling the revised Bethesda guidelines (RBG), defined as RBG-compatible cases. We analyzed germline variants in 21 genes related to a hereditary predisposition for cancer as well as clinical features in all 20 cases. Results: The RBG-compatible cases did not show any unique clinicopathological features. Targeted sequencing data revealed three patients carrying deleterious or likely deleterious variants. Specifically, these three patients harbored a nonsense variant in ATM, a frameshift variant in ATM, and a concurrent nonsense variant in PMS2 and missense variant in CHEK2 (double-mutation carrier), respectively. Although an MMR gene mutation was identified in only one of the 20 patients, up to 15% of the RBG-compatible PC cases were associated with germline deleterious or likely deleterious variants. Conclusions: These findings showed that these guidelines could be useful for identifying PC patients with DNA damage repair genes as well as MMR genes.
KW - DNA mismatch repair genes
KW - Germline variants
KW - Lynch syndrome
KW - Pancreatic cancer
KW - Revised Bethesda guidelines
UR - https://www.scopus.com/pages/publications/85045481124
U2 - 10.1007/s00535-018-1466-y
DO - 10.1007/s00535-018-1466-y
M3 - Article
C2 - 29667044
AN - SCOPUS:85045481124
SN - 0944-1174
VL - 53
SP - 1159
EP - 1167
JO - Journal of Gastroenterology
JF - Journal of Gastroenterology
IS - 10
ER -