TY - JOUR
T1 - Advances and Challenges of the Decade
T2 - The Ever-Changing Clinical and Genetic Landscape of Immunodeficiency
AU - Walter, Jolan E.
AU - Ziegler, John B.
AU - Ballow, Mark
AU - Cunningham-Rundles, Charlotte
N1 - Funding Information:
Conflicts of interest: J.E. Walter has received grant support from Takeda , Janssen , Chiesi , Mustang Bio , ADMA Biologicals , Octapharma, X4- Pharmaceuticals , Novartis , Regeneron , and Bristol-Myers Squibb . She has been a consultant or participated in advisory boards for Takeda, X4 Pharmaceuticals, CSL-Behring, Grifols, ADMA Biologicals, Enzyvant, and Regeneron; and participated in a speaker's bureau for Takeda; and has received royalties from UpToDate. M. Ballow has received honoraria from CSL Behring and UpToDate; has served as a consultant or on an advisory board for CSL Behring, Grifols, and Takeda; has been a member of independent data monitoring committees for Alladapt, Green Cross, GlaxoSmithKline, Ichnos Sciences, and Pharming LLC; and has served as a consultant medical director for the Immune Deficiency Foundation. C. C.-R. has research funding support from the National Institutes of Health (AI 101093, AI-086037, and AI-48693) and the David S Gottesman Chair. She has been an advisor to the Pharming Group, X4 Pharmaceuticals, and Takeda Pharmaceuticals and has taken part in research studies with CSL-Behring, Regeneron, and Jounce Therapeutics. The rest of the authors declare that they have no relevant conflicts of interest.
Funding Information:
C. Cunningham-Rundles received research funding support from the National Institutes of Health (grants nos. AI-101093, AI-086037, and AI-48693). J. E. Walter received research funding support from the National Institutes of Health (grant no. R01AI153830).
Publisher Copyright:
© 2022 American Academy of Allergy, Asthma & Immunology
PY - 2023/1
Y1 - 2023/1
N2 - In the past 10 years, we have witnessed major advances in clinical immunology. Newborn screening for severe combined immunodeficiency has become universal in the United States and screening programs are being extended to severe combined immunodeficiency and other inborn errors of immunity globally. Early genetic testing is becoming the norm for many of our patients and allows for informed selection of targeted therapies including biologics repurposed from other specialties. During the COVID-19 pandemic, our understanding of essential immune responses expanded and the discovery of immune gene defects continued. Immunoglobulin products, the backbone of protection for antibody deficiency syndromes, came into use to minimize side effects. New polyclonal and monoclonal antibody products emerged with increasing options to manage respiratory viral agents such as SARS-CoV-2 and respiratory syncytial virus. Against these advances, we still face major challenges. Atypical is becoming typical as phenotypes of distinct genetic disease overlap whereas the clinical spectrum of the same genetic defect widens. Therefore, clinical judgment needs to be paired with repeated deep immune phenotyping and upfront genetic testing, as technologies rapidly evolve, and clinical disease often progresses with age. Managing patients with organ damage resulting from immune dysregulation poses a special major clinical challenge and management often lacks standardization, from autoimmune cytopenias, granulomatous interstitial lung disease, enteropathy, and liver disease to endocrine, rheumatologic, and neurologic complications. Clinical, translational, and basic science networks will continue to advance the field; however, cross-talk and education with practicing allergists/immunologists are essential to keep up with the ever-changing clinical and genetic landscape of inborn errors of immunity.
AB - In the past 10 years, we have witnessed major advances in clinical immunology. Newborn screening for severe combined immunodeficiency has become universal in the United States and screening programs are being extended to severe combined immunodeficiency and other inborn errors of immunity globally. Early genetic testing is becoming the norm for many of our patients and allows for informed selection of targeted therapies including biologics repurposed from other specialties. During the COVID-19 pandemic, our understanding of essential immune responses expanded and the discovery of immune gene defects continued. Immunoglobulin products, the backbone of protection for antibody deficiency syndromes, came into use to minimize side effects. New polyclonal and monoclonal antibody products emerged with increasing options to manage respiratory viral agents such as SARS-CoV-2 and respiratory syncytial virus. Against these advances, we still face major challenges. Atypical is becoming typical as phenotypes of distinct genetic disease overlap whereas the clinical spectrum of the same genetic defect widens. Therefore, clinical judgment needs to be paired with repeated deep immune phenotyping and upfront genetic testing, as technologies rapidly evolve, and clinical disease often progresses with age. Managing patients with organ damage resulting from immune dysregulation poses a special major clinical challenge and management often lacks standardization, from autoimmune cytopenias, granulomatous interstitial lung disease, enteropathy, and liver disease to endocrine, rheumatologic, and neurologic complications. Clinical, translational, and basic science networks will continue to advance the field; however, cross-talk and education with practicing allergists/immunologists are essential to keep up with the ever-changing clinical and genetic landscape of inborn errors of immunity.
KW - Immune dysregulation
KW - Immunoglobulin
KW - Inborn error of immunity
KW - Newborn screening
KW - Severe combined immunodeficiency
UR - http://www.scopus.com/inward/record.url?scp=85145301046&partnerID=8YFLogxK
U2 - 10.1016/j.jaip.2022.11.007
DO - 10.1016/j.jaip.2022.11.007
M3 - Article
AN - SCOPUS:85145301046
SN - 2213-2198
VL - 11
SP - 107
EP - 115
JO - Journal of Allergy and Clinical Immunology: In Practice
JF - Journal of Allergy and Clinical Immunology: In Practice
IS - 1
ER -